Adrenoleukodystrophy in a Nigerian boy: A case report and review of literature

Authors

  • Akowundu Pauline Karachi Department of Paediatrics
  • Opoola Zainab Aramide Department of Paediatrics
  • Ibrahim Usman Olaitan Department of Paediatrics
  • Lesi Foluso Afolabi Department of Paediatrics

Abstract

Abstract: Adrenoleukodystrophy (ALD) is a hereditary, X-linked metabolic disorder with autosomal recessive traits. It arises
from mutation in ABCD1 gene on chromosome Xq28. This mutation leads to demyelination of the nervous system, adrenal insufficiency and accumulation of Long Chain Fatty Acids (LCFA). The long chain fatty acids accumulates in tissues throughout the body but the most severely affected tissues are the myelin in the central nervous system, the adrenal cortex and the Leydig cells in the testes. The phenotypic presentations are highly variable which may lead to delayed recognition and misdiagnosis. Most young patients with ALD develop seizures and progressive neurological deficits. It may initially manifest with alterations of behaviour, hearing, vision, speech, gait and in more advanced cases, it results in generalized hypertension, dysphagia and loss of
cognitive and motor function. We report a case of adrenoleukodystrophy in a Nigerian boy and also review the existing literature on the condition to increase the awareness and knowledge of this disorder.

Keywords; Adrenoleukodystrophy, Nigerian boy, Case report

Author Biographies

  • Akowundu Pauline Karachi, Department of Paediatrics

    Lagos University Teaching
    Hospital, Idi-Araba
    Lagos, Nigeria

  • Opoola Zainab Aramide, Department of Paediatrics

    Lagos University Teaching
    Hospital, Idi-Araba
    Lagos, Nigeria

  • Ibrahim Usman Olaitan, Department of Paediatrics

    Lagos University Teaching
    Hospital, Idi-Araba
    Lagos, Nigeria

  • Lesi Foluso Afolabi, Department of Paediatrics

    College of Medicine, University of
    Lagos, Lagos, Nigeria.

Published

2021-08-22

How to Cite

Adrenoleukodystrophy in a Nigerian boy: A case report and review of literature. (2021). NIGERIAN JOURNAL OF PAEDIATRICS, 48(4), 215 – 218. https://www.njpaediatrics.com/index.php/njp/article/view/9